IJOHNS  Vol.2 No.1 , January 2013
Emergency Airway Obstruction in Newborn Due to Congenital Saccular Cyst
Abstract: Laryngeal cyst causing neonatal airway obstruction during labor is a very rare condition [1]. Congenital laryngeal cysts are a rare cause of neonatal airway obstruction. Traditionally, these cysts have been treated surgically by endoscopic excision or marsupialization. However, the cyst often extends beyond the larynx. We describe a case of a newborn that, during delivery, became cyanotic due to airway obstruction and respiratory distress. To the best of our knowledge this is the first report of a saccular cyst obstructing airway during birth prior to intubation. The immediate and late treatments together with a literature review are described.

Cite this paper: I. Braverman, G. Avior, M. Feldman, A. Gubarev, R. Stein, H. Ras and A. Zeina, "Emergency Airway Obstruction in Newborn Due to Congenital Saccular Cyst," International Journal of Otolaryngology and Head & Neck Surgery, Vol. 2 No. 1, 2013, pp. 34-38. doi: 10.4236/ijohns.2013.21009.

[1]   V. Forte, G. Fuoco and A. James, “A New Classification System for Congenital Laryngeal Cysts,” Laryngoscope, Vol. 114, No. 6, 2004, pp. 1123-1127. doi:10.1097/00005537-200406000-00031

[2]   A. L. Abramson and B. Zielinski, “Congenital Saccular Cysts of the Newborn,” Laryngoscope, Vol. 94, No. 12, 1984, pp. 1580-1581. doi:10.1288/00005537-198412000-00009

[3]   P. H. Holinger, L. D. Holinger, D. R. Barnes and L. J. Smid, “Laryngocele and Saccular Cysts,” Annals of Otology, Vol. 87, No. 5, 1978, pp. 675-685.

[4]   L. W. Desanto, K. D. Devine, L. H. Weiland, “Cysts of the Larynx, Classification,” Laryngoscope, Vol. 80, No. 1, 1970, pp. 261-267. doi:10.1288/00005537-197001000-00013

[5]   C. Arens, H. Glanz and O. Kleinsasser, “Clinical and Morphological Aspects of Laryngeal Cysts,” European Archives of Oto-Rhino-Laryngology, Vol. 254, No. 9-10, 1997, pp. 430-436. doi:10.1007/BF02439974

[6]   S. M. Ahmad and A. M. Soliman, “Congenital Anomalies of the Larynx,” Otolaryngologic Clinics of North America, Vol. 40, No. 1, 2007, pp. 177-191. doi:10.1016/j.otc.2006.10.004

[7]   D. J. Kirse, C. J. Rees, A. W. Celmer, D. E. Bruegger, “Endoscopic Extended Ventriculotomy for Congenital Saccular Cysts of the Larynx in Infants,” Archives of Otolaryngology—Head & Neck Surgery, Vol. 132, No. 7, 2006, pp. 724-728. doi:10.1001/archotol.132.7.724

[8]   C. A. Righini, H. Kadaoui, N. Morel, C. Llerena, E. Reyt, “Stridor in a Newborn Caused by a Congenital Laryngeal Saccular Cyst,” International Journal of Pediatric Otorhinolaryngology Extra, Vol. 1, No. 2, 2006, pp. 145-149. doi:10.1016/j.pedex.2006.03.005

[9]   I. Khodaei, A. Karkanevatos, A. Poulios and M. S. McCormick, “Airway Obstruction in a Newborn Due to a Congenital Laryngeal Cyst,” International Journal of Pediatric Otorhinolaryngology Extra, Vol. 2, No. 4, 2007, pp. 254-256. doi:10.1016/j.pedex.2007.08.001

[10]   E. Ostfeld, Z. Hazan, S. Rabinson and L. Auslander, “Surgical Management of Congen Ital Supraglottic Lateral Saccular Cyst,” International Journal of Pediatric Otorhinolaryngology, Vol. 19, No. 3, 1990, pp. 289-294. doi:10.1016/0165-5876(90)90010-O

[11]   Z. Hazan, E. Ostfeld, S. Rabinson and L. Auslander, “Neonatal Respiratory Distress Due to Congenital Laryngeal Cyst,” Harefuah, Vol. 119, No. 11, 1990, pp. 371-372.

[12]   F. Tosun, H. S?ken and Y. Ozkaptan, “Saccular Cyst in an Infant, an Unusual Cause of Life-Threatening Stridor and Its Surgical Treatment,” The Turkish Journal of Pediatrics, Vol. 48, No. 2, 2006, pp. 178-80.

[13]   R. J. Pennings, F. J. van den Hoogen and H. A. Marres, “Giant Laryngoceles, a Cause of Upper Airway Obstruction,” European Archives of Oto-Rhino-Laryngology, Vol. 258, No. 3, 2001, pp. 137-140. doi:10.1007/s004050100316

[14]   H. M. Danish, R. J. Meleca, J. P. Dworkin and T. R. Abbarah, “Laryngeal Obstructing Saccular Cysts, a Review of This Disease and Treatment Approach Emphasizing Complete Endoscopic Carbon Dioxide Laser Excision,” Archives of Otolaryngology—Head & Neck Surgery, Vol. 124, No. 5, 1998, pp. 593-6.

[15]   E. Silingardi, N. Sola, A. L. Santunione and N. Trani, “Lateral Saccular Laryngeal Cyst and Unexpected Asphyxial Death,” Forensic Science International, Vol. 206, No. 1-3, 2011, pp. e17-e19.

[16]   T. K. Kastowsky, M. P. Stevenson and J. A. Dufou, “Sudden Death from Saccular Laryngeal Cyst,” Journal of Forensic Sciences, Vol. 51, No. 5, 2006, pp. 1144-1146. doi:10.1007/s004050100316

[17]   V. Forte, J. Warshawski, P. Thorner and S. Conley, “Unusual Laryngeal Cysts in the Newborn,” International Journal of Pediatric Otorhinolaryngology, Vol. 37, No. 3, 1996, pp. 261-267. doi:10.1016/0165-5876(96)01407-3

[18]   M. H. Thabet and H. Kotob, “Lateral Saccular Cysts of the Larynx. Aetiology, Diagnosis and Management,” The Journal of Laryngology & Otology, Vol. 115, No. 4, 2001, pp. 293-297. doi:10.1258/0022215011907488